Phenotype Details
Phene ID
1200
Name
Mannosidosis, beta
Phene Name
N/A
OMIA ID
626
Species ID
9913
Characterised
Yes
Characterised Year
1999
Linked Genes
SymbolGene IDChromosomeDescription
MANBA2819096mannosidase beta
Linked Variants
Variant IDPhenotypeGene IDDeleteriousChromosomeGenomicTranscriptProtein
297Mannosidosis, beta28190916NC_037333.1:g.22188765G>ANM_174387.2:c.2574G>ANP_776812.1:p.(W858*)
Linked Breeds
BreedBreed IDSpecies IDVBO Term
Salers (Cattle)2579913http://purl.obolibrary.org/obo/VBO_0000366
Summary

Abbitt et al. (1991) reported that bovine beta-mannosidosis, a lysosomal storage disease, is caused by a deficiency of beta-mannosidase. Affected neonatal calves are unable to rise with intention tremors, hidebound skin, slightly domed calvaria, slight prognathism, and narrow palpebral fissures. Their postmortem findings included variable dilatation of the lateral cerebral ventricles, marked pallor and paucity of white matter of the cerebrum and cerebellum, and mild to marked bilateral renomegaly. Lovell et al (1991) reported that in bovine beta-mannosidosis, the thyroid in the affected newborn shows marked cytoplasmic vacuolation, with an associated reduction in the serum concentrations of thyroxine and tri-iodothyronine (Mohammad Shariflou 3/11/2006).

Molecular Genetics

By cloning and sequencing a very likely comparative candidate gene (based on the homologous human disorder), Leipprandt et al. (1999) reported a G to A transition at position 2574 of the cDNA coding sequence of the MANBA gene, resulting in a premature stop codon near the 3' end of the coding region. They described a PCR test for detecting this mutation (Mohammad Shariflou 3/11/2006; FN 15/9/2012).

Back to Phenotypes