Phenotype Details
Phene ID
2971
Name
Caprine-like generalized hypoplasia syndrome
Phene Name
Syndrome d'Hypoplasie Généralisée Capréoliforme. Also known as Seckel-like syndrome
OMIA ID
1502
Species ID
9913
Characterised
Yes
Characterised Year
2015
Linked Variants
Variant IDPhenotypeGene IDDeleteriousChromosomeGenomicTranscriptProtein
964Caprine-like Generalized Hypoplasia Syndrome388266233113g.64710424C>Tc.493C>Tp.(Q165*)
Linked Breeds
BreedBreed IDSpecies IDVBO Term
Montbéliarde (Cattle)1629913http://purl.obolibrary.org/obo/VBO_0000306
Molecular Genetics

Nonsense mutation: c.493C>T "at position 65,369,074 in [exon 4 of] the CEP250 gene" "that encodes the centrosomal protein C-Nap1". The mutation "solely affects centrosome cohesion". "Loss of C-Nap1-mediated centriole cohesion leads to an altered cell migration phenotype". Results and quotations from Floriot et al. (2015).

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